Abstract:

Unicystic ameloblastoma a rare variant of ameloblastoma accounting for 6 % of ameloblastomas is characterized by slow growth and is less aggressive in comparison with ameloblastoma. It is commonly associated with an impacted third molar. However, under rare circumstances it may be associated with impacted mandibular canine.  We present a case of unicystic ameloblastoma in a 31-year-old female patient associated with an impacted mandibular canine. Following treatment, the patient’s sister underwent routine radiographic examination which revealed impacted tooth no 43, a finding exactly similar to her sister's case and a small radiolucency surrounding the crown of tooth no 43 which was surgically extracted to prevent further complications. Both the patients are currently under follow-up.  With the available clinical data, we hypothesize that the occurrence of jaw lesions associated with impacted teeth could be familial. The present cases highlight the importance of routine radiographic examination and follows up and to obtain family history and screen the family members of patients with impacted teeth to prevent potential complications.

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